Molecule

NLRP3 (Cryopyrin)

Inflammasome sensor and scaffold

Expression change
mutated
Evidence level
established
Targeted by
MCC950, Dapansutrile (experimental)

Role in pathogenesis

Gain-of-function mutations in NLRP3 cause constitutive or hyper-responsive inflammasome assembly, bypassing normal signal 2 requirement. Over 250 pathogenic variants identified, mostly in exon 3 encoding the NACHT domain.

Targeting drugs (1)

DrugMechanismResponse rateLine
DapansutrileOral NLRP3 inflammasome inhibitorPhase 2a (no CAPS efficacy data yet)Experimental

Sources (3)

A1Hoffman HM et al. (2001) Mutation of a new gene encoding a putative pyrin-like protein causes familial cold autoinflammatory syndrome and Muckle-Wells syndromePubMed
B2Molina-López C et al. (2024) Pathogenic NLRP3 mutants form constitutively active inflammasomes resulting in immune-metabolic limitation of IL-1β productionPubMed
B4Booshehri LM et al. (2019) CAPS and NLRP3PubMed